Defective endothelial cell migration in the absence of Cdc42 leads to capillary-venous malformations

Research output: Contribution to journalJournal articleResearchpeer-review

  • Bàrbara Laviña
  • Marco Castro
  • Colin Niaudet
  • Bert Cruys
  • Alberto Álvarez-Aznar
  • Peter Carmeliet
  • Katie Bentley
  • Brakebusch, Cord Herbert
  • Christer Betsholtz
  • Konstantin Gaengel

Formation and homeostasis of the vascular system requires several coordinated cellular functions, but their precise interplay during development and their relative importance for vascular pathologies remain poorly understood. Here, we investigated the endothelial functions regulated by Cdc42 and their in vivo relevance during angiogenic sprouting and vascular morphogenesis in the postnatal mouse retina. We found that Cdc42 is required for endothelial tip cell selection, directed cell migration and filopodia formation, but dispensable for cell proliferation or apoptosis. Although the loss of Cdc42 seems generally compatible with apical-basal polarization and lumen formation in retinal blood vessels, it leads to defective endothelial axial polarization and to the formation of severe vascular malformations in capillaries and veins. Tracking of Cdc42-depleted endothelial cells in mosaic retinas suggests that these capillary-venous malformations arise as a consequence of defective cell migration, when endothelial cells that proliferate at normal rates are unable to re-distribute within the vascular network.

Original languageEnglish
Article numberdev161182
JournalDevelopment (Cambridge, England)
Volume145
Issue number13
Number of pages20
ISSN0950-1991
DOIs
Publication statusPublished - 2 Jul 2018

ID: 199342210